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Meconium ileus in a Lebanese family secondary to mutations in the GUCY2C gene.

Authors :
Smith A
Bulman DE
Goldsmith C
Bareke E
Majewski J
Boycott KM
Nikkel SM
Source :
European journal of human genetics : EJHG [Eur J Hum Genet] 2015 Jul; Vol. 23 (7), pp. 990-2. Date of Electronic Publication: 2014 Nov 05.
Publication Year :
2015

Abstract

Meconium ileus is most often associated with mutations in the CFTR gene; however recently, mutations in GUCY2C in the Bedouin population have also been shown to result in this phenotype. This gene codes for an intestinal transmembrane receptor that generates cyclic GMP, which activates cystic fibrosis transmembrane receptor. We report a third family that supports the association of variants in the GUCY2C gene with meconium ileus (MI). A Lebanese kindred was studied and individuals affected with MI had either homozygous or compound heterozygous variants in GUCY2C. The earliest manifestation of the affected individuals was the presence of second trimester fetal echogenic bowel, thus resulting in the expansion of the differential diagnosis of this ultrasound finding.

Details

Language :
English
ISSN :
1476-5438
Volume :
23
Issue :
7
Database :
MEDLINE
Journal :
European journal of human genetics : EJHG
Publication Type :
Academic Journal
Accession number :
25370039
Full Text :
https://doi.org/10.1038/ejhg.2014.236