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Report of a case of Raine syndrome and literature review.

Authors :
Seidahmed MZ
Alazami AM
Abdelbasit OB
Al Hussein K
Miqdad AM
Abu-Sa'da O
Mustafa T
Bahjat S
Alkuraya FS
Source :
American journal of medical genetics. Part A [Am J Med Genet A] 2015 Oct; Vol. 167A (10), pp. 2394-8. Date of Electronic Publication: 2015 May 14.
Publication Year :
2015

Abstract

We report on a case of Raine syndrome with a mutation in FAM20C and typical phenotypic features consisting of midface hypoplasia, hypoplastic nose, choanal atresia, wide fontanelle, exophthalmos, generalized osteosclerosis and intracranial calcification. New features in our patient are cerebellar hypoplasia and pachygyria. We review the literature and conclude that the triad of hypoplastic nose, exophthalmos and generalized osteosclerosis and/or intracranial calcification is consistent in all molecularly confirmed cases.<br /> (© 2015 Wiley Periodicals, Inc.)

Details

Language :
English
ISSN :
1552-4833
Volume :
167A
Issue :
10
Database :
MEDLINE
Journal :
American journal of medical genetics. Part A
Publication Type :
Academic Journal
Accession number :
25974638
Full Text :
https://doi.org/10.1002/ajmg.a.37159