Back to Search
Start Over
Clinical evaluation and molecular screening of a large consecutive series of albino patients.
- Source :
-
Journal of human genetics [J Hum Genet] 2017 Feb; Vol. 62 (2), pp. 277-290. Date of Electronic Publication: 2016 Oct 13. - Publication Year :
- 2017
-
Abstract
- Oculocutaneous albinism (OCA) is characterized by hypopigmentation of the skin, hair and eye, and by ophthalmologic abnormalities caused by a deficiency in melanin biosynthesis. In this study we recruited 321 albino patients and screened them for the genes known to cause oculocutaneous albinism (OCA1-4 and OCA6) and ocular albinism (OA1). Our purpose was to detect mutations and genetic frequencies of the main causative genes, offering to albino patients an exhaustive diagnostic assessment within a multidisciplinary approach including ophthalmological, dermatological, audiological and genetic evaluations. We report 70 novel mutations and the frequencies of the major causative OCA genes that are as follows: TYR (44%), OCA2 (17%), TYRP1 (1%), SLC45A2 (7%) and SLC24A5 (<0.5%). An additional 5% of patients had GPR143 mutations. In 19% of cases, a second reliable mutation was not detected, whereas 7% of our patients remain still molecularly undiagnosed. This comprehensive study of a consecutive series of OCA/OA1 patients allowed us to perform a clinical evaluation of the different OCA forms.
- Subjects :
- Adult
Aged
Genetic Testing
Humans
Male
Melanins biosynthesis
Middle Aged
Albinism, Oculocutaneous diagnosis
Albinism, Oculocutaneous genetics
Antigens, Neoplasm genetics
Antiporters genetics
Eye Proteins genetics
Membrane Glycoproteins genetics
Membrane Proteins genetics
Membrane Transport Proteins genetics
Oxidoreductases genetics
Subjects
Details
- Language :
- English
- ISSN :
- 1435-232X
- Volume :
- 62
- Issue :
- 2
- Database :
- MEDLINE
- Journal :
- Journal of human genetics
- Publication Type :
- Academic Journal
- Accession number :
- 27734839
- Full Text :
- https://doi.org/10.1038/jhg.2016.123