Back to Search
Start Over
A novel Lynch syndrome pedigree bearing germ-line MSH2 missense mutation c.1808A>T (Asp603Val)
- Source :
- Japanese Journal of Clinical Oncology. 52:81-85
- Publication Year :
- 2021
- Publisher :
- Oxford University Press (OUP), 2021.
-
Abstract
- We report the first pedigree of Lynch syndrome bearing a germ-line MSH2 missense mutation c.1808A>T (Asp603Val). Until now, this missense mutation, in exon 12 of MSH2, was identified as a variant of unknown significance in the International Society for Gastrointestinal Hereditary Tumours database. In vitro induction mutagenesis experiments indicated that the MSH2 mutant protein (Asp603Val) is easily degraded in embryonic stem cells, albeit there is no clinical information concerning this mutant. Our pedigree includes four patients with Lynch syndrome-associated malignancies and clinically matches the Amsterdam II criteria. The proband, a female, first had an endometrial cancer at the age of 49 and then mantle cell lymphoma, colonic and gastric adenocarcinomas and neuroendocrine carcinoma, successively. Her mother also had Lynch syndrome-associated malignancies, including colonic, uterine and gastric cancers, and her elder son had rectal cancer. In the germline of the proband and her son, an MSH2 missense mutation c.1808A>T was discovered. Immunohistochemical analyses indicated that the expression of the MSH2 protein was decreased in the tumors, such as gastric cancer and neuroendocrine carcinoma, due to the missense mutation c.1808A>T. This study showed that the MSH2 missense mutation c.1808A>T (Asp603Val) is a likely pathogenic mutation and is responsible for typical Lynch syndrome-associated malignancies, including neuroendocrine carcinoma.
- Subjects :
- Male
Proband
congenital, hereditary, and neonatal diseases and abnormalities
Cancer Research
Mutation, Missense
Mutant protein
Humans
Medicine
Missense mutation
Radiology, Nuclear Medicine and imaging
Germ-Line Mutation
business.industry
Endometrial cancer
nutritional and metabolic diseases
Cancer
General Medicine
Middle Aged
medicine.disease
Colorectal Neoplasms, Hereditary Nonpolyposis
digestive system diseases
Lynch syndrome
Pedigree
Germ Cells
MutS Homolog 2 Protein
Oncology
MSH2
Mutation (genetic algorithm)
Cancer research
Female
MutL Protein Homolog 1
business
Subjects
Details
- ISSN :
- 14653621
- Volume :
- 52
- Database :
- OpenAIRE
- Journal :
- Japanese Journal of Clinical Oncology
- Accession number :
- edsair.doi.dedup.....20eb6abfb254e2e73b34b35350f53099
- Full Text :
- https://doi.org/10.1093/jjco/hyab173