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Production and characterization of CSSI003 (2961) human induced pluripotent stem cells (iPSCs) carrying a novel puntiform mutation in RAI1 gene, Causative of Smith–Magenis syndrome

Authors :
Giuseppe Lamorte
Jessica Rosati
Daniela Ferrari
Laura Bernardini
Gianluigi Mazzoccoli
Matteo Della Monica
Angelo L. Vescovi
Antonella De Jaco
Elisa Maria Turco
Annamaria Nardone
Ersilia Vinci
Filomena Altieri
Barbara Torres
Altieri, F
Turco, E
Vinci, E
Torres, B
Ferrari, D
De Jaco, A
Mazzoccoli, G
Lamorte, G
Nardone, A
Della Monica, M
Bernardini, L
Vescovi, A
Rosati, J
Source :
Stem Cell Research, Vol 28, Iss, Pp 153-156 (2018)
Publication Year :
2018
Publisher :
Elsevier BV, 2018.

Abstract

Smith-Magenis syndrome (SMS) is a complex genetic disorder characterized by developmental delay, behavioural problems and circadian rhythm dysregulation. About 90% of SMS cases are due to a 17p11.2 deletion containing retinoic acid induced1 (RAI1) gene, 10% are due to heterozygous mutations affecting RAI1 coding region. Little is known about RAI1 role.

Details

ISSN :
18735061
Volume :
28
Database :
OpenAIRE
Journal :
Stem Cell Research
Accession number :
edsair.doi.dedup.....2a085952af3911fae3616d629973c25d
Full Text :
https://doi.org/10.1016/j.scr.2018.02.016