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Clinical Considerations for a Family with Dilated Cardiomyopathy, Sudden Cardiac Death, and a Novel TTN Frameshift Mutation

Authors :
Michelle M. Monasky
Marco Piccoli
Giuseppe Ciconte
Andrea Bernardini
Carlo Pappone
Emanuele Micaglio
Valerio Mecarocci
Luigi Anastasia
Andrea Ghiroldi
Emanuela T Locati
Valeria Borrelli
Micaglio, E.
Monasky, M. M.
Bernardini, A.
Mecarocci, V.
Borrelli, V.
Ciconte, G.
Locati, E. T.
Piccoli, M.
Ghiroldi, A.
Anastasia, L.
Pappone, C.
Source :
International Journal of Molecular Sciences, International Journal of Molecular Sciences, Vol 22, Iss 670, p 670 (2021)
Publication Year :
2021
Publisher :
MDPI AG, 2021.

Abstract

Dilated cardiomyopathy (DCM) is the leading indication for heart transplantation. TTN gene truncating mutations account for about 25% of familial DCM cases and for 18% of sporadic DCM cases. The clinical relevance of specific variants in TTN has been difficult to determine because of the sheer size of the protein for which TTN encodes, as well as existing extensive genetic variation. Clinicians should communicate novel clinically-relevant variants and genotype–phenotype associations, so that animal studies evaluating the molecular mechanisms are always conducted with a focus on clinical significance. In the present study, we report for the first time the novel truncating heterozygous variant NM_001256850.1:c.72777_72783del (p.Phe24259Leufs*51) in the TTN gene and its association with DCM in a family with sudden death. This variant occurs in the A-band region of the sarcomere, in a known mutational hotspot of the gene. Truncating titin variants that occur in this region are the most common cause of DCM and have been rarely reported in asymptomatic individuals, differently from other pathogenic TTN gene variants. Further studies are warranted to better understand this particular clinically-relevant variant.

Details

ISSN :
14220067
Volume :
22
Database :
OpenAIRE
Journal :
International Journal of Molecular Sciences
Accession number :
edsair.doi.dedup.....3110c3c81b0d83dcb4e8d536f35fbb2f
Full Text :
https://doi.org/10.3390/ijms22020670