Back to Search Start Over

A large scale hearing loss screen reveals an extensive unexplored genetic landscape for auditory dysfunction

Authors :
Bowl, Michael R.
Simon, Michelle M.
Ingham, Neil J.
Greenaway, Simon
Santos, Luis
Cater, Heather
Taylor, Sarah
Mason, Jeremy
Kurbatova, Natalja
Pearson, Selina
Bower, Lynette R.
Clary, Dave A.
Meziane, Hamid
Reilly, Patrick
Minowa, Osamu
Kelsey, Lois
Allen, Sue
Clementson-Mobbs, Sharon
Codner, Gemma
Fray, Martin
Gardiner, Wendy
Joynson, Russell
Kenyon, Janet
Loeffler, Jorik
Nell, Barbara
Parker, Andrew
Quwailid, Deen
Stewart, Michelle
Walling, Alison
Zaman, Rumana
Chen, Chao Kung
Conte, Nathalie
Matthews, Peter
Relac, Mike
Tudose, Ilinca
Warren, Jonathan
Le Marchand, Elise
El Amri, Amal
El Fertak, Leila
Ennah, Hamid
Ali-Hadji, Dalila
Ayadi, Abdel
Wattenhofer-Donze, Marie
Moulaert, David
Jacquot, Sylvie
André, Philippe
Birling, Marie Christine
Pavlovic, Guillaume
Lalanne, Valérie
Lux, Aline
Riet, Fabrice
Mittelhaeuser, Christophe
Bour, Raphael
Guimond, Alain
Bam'Hamed, Chaouki
Leblanc, Sophie
Vasseur, Laurent
Selloum, Mohammed
Sorg, Tania
Ayabe, Shinya
Furuse, Tamio
Kaneda, Hideki
Kobayashi, Kimio
Masuya, Hiroshi
Miura, Ikuo
Obata, Yuichi
Suzuki, Tomohiro
Tamura, Masaru
Tanaka, Nobuhiko
Yamada, Ikuko
Yoshiki, Atsushi
Berberovic, Zorana
Bubshait, Mohammed
Cabezas, Jorge
Carroll, Tracy
Clark, Greg
Clarke, Shannon
Creighton, Amie
Danisment, Ozge
Eskandarian, Mohammad
Feugas, Patricia
Gertsenstein, Marina
Guo, Ruolin
Hunter, Jane
Jacob, Elsa
Lan, Qing
Laurin, Valerie
Law, Napoleon
MacMaster, Sue
Miller, David
Morikawa, Lily
Newbigging, Susan
Owen, Celeste
Penton, Patricia
Pereira, Monica
Qu, Dawei
Shang, Xueyuan
Sleep, Gillian
Sohel, Khondoker
Tondat, Sandra
Wang, Yanchun
Vukobradovic, Igor
Zhu, Yingchun
Chiani, Francesco
Di Pietro, Chiara
Di Segni, Gianfranco
Ermakova, Olga
Ferrara, Filomena
Fruscoloni, Paolo
Gambadoro, Aalessia
Gastaldi, Serena
Golini, Elisabetta
Sala, Gina La
Mandillo, Silvia
Marazziti, Daniela
Massimi, Marzia
Matteoni, Rafaele
Orsini, Tiziana
Pasquini, Miriam
Raspa, Marcello
Rauch, Aline
Rossi, Gianfranco
Rossi, Nicoletta
Putti, Sabrina
Scavizzi, Ferdinando
Tocchini-Valentini, Giuseppe D.
Beig, Joachim
Bürger, Antje
Giesert, Florian
Graw, Jochen
Kühn, Ralf
Oritz, Oskar
Schick, Joel
Seisenberger, Claudia
Amarie, Oana
Garrett, Lillian
Hölter, Sabine M.
Zimprich, Annemarie
Aguilar-Pimentel, Antonio
Beckers, Johannes
Brommage, Robert
Calzada-Wack, Julia
Fuchs, Helmut
Gailus-Durner, Valérie
Lengger, Christoph
Leuchtenberger, Stefanie
Maier, Holger
Marschall, Susan
Moreth, Kristin
Neff, Frauke
Östereicher, Manuela A.
Rozman, Jan
Steinkamp, Ralph
Stoeger, Claudia
Treise, Irina
Stoeger, Tobias
Yildrim, Ali Önder
Eickelberg, Oliver
Becker, Lore
Klopstock, Thomas
Ollert, Markus
Busch, Dirk H.
Schmidt-Weber, Carsten
Bekeredjian, Raffi
Zimmer, Andreas
Rathkolb, Birgit
Wolf, Eckhard
Klingenspor, Martin
Tocchini-Valentini, Glauco P.
Gao, Xiang
Bradley, Allan
Skarnes, William C.
Moore, Mark
Beaudet, Arthur L.
Justice, Monica J.
Seavitt, John
Dickinson, Mary E.
Wurst, Wolfgang
De Angelis, Martin Hrabe
Herault, Yann
Wakana, Shigeharu
Nutter, Lauryl M.J.
Flenniken, Ann M.
McKerlie, Colin
Murray, Stephen A.
Svenson, Karen L.
Braun, Robert E.
West, David B.
Lloyd, K. C.Kent
Adams, David J.
White, Jacqui
Karp, Natasha
Flicek, Paul
Smedley, Damian
Meehan, Terrence F.
Parkinson, Helen E.
Teboul, Lydia M.
Wells, Sara
Steel, Karen P.
Mallon, Ann Marie
Brown, Steve D.M.
Mason, Jeremy [0000-0002-2796-5123]
de Angelis, Martin Hrabe [0000-0002-7898-2353]
Herault, Yann [0000-0001-7049-6900]
Wakana, Shigeharu [0000-0001-8532-0924]
McKerlie, Colin [0000-0002-2232-0967]
Lloyd, KC Kent [0000-0002-5318-4144]
Flicek, Paul [0000-0002-3897-7955]
Smedley, Damian [0000-0002-5836-9850]
Apollo - University of Cambridge Repository
Source :
Nat. Commun. 8:886 (2017), Nature Communications, Vol 8, Iss 1, Pp 1-11 (2017), Nature Communications, Bowl, M R, Simon, M M, Ingham, N J, Greenaway, S, Santos, L, Cater, H, Taylor, S, Mason, J, Kurbatova, N, Pearson, S, Bower, L R, Clary, D A, Meziane, H, Reilly, P, Minowa, O, Kelsey, L, Allen, S, Clementson-Mobbs, S, Codner, G, Fray, M, Gardiner, W, Joynson, R, Kenyon, J, Loeffler, J, Nell, B, Parker, A, Quwailid, D, Stewart, M, Walling, A, Zaman, R, Chen, C K, Conte, N, Matthews, P, Relac, M, Tudose, I, Warren, J, Le Marchand, E, El Amri, A, El Fertak, L, Ennah, H, Ali-Hadji, D, Ayadi, A, Wattenhofer-Donze, M, Moulaert, D, Jacquot, S, André, P, Birling, M C, Pavlovic, G, Lalanne, V, Lux, A, Riet, F, Mittelhaeuser, C, Bour, R, Guimond, A, Bam'Hamed, C, Leblanc, S, Vasseur, L, Selloum, M, Sorg, T, Ayabe, S, Furuse, T, Kaneda, H, Kobayashi, K, Masuya, H, Miura, I, Obata, Y, Suzuki, T, Tamura, M, Tanaka, N, Yamada, I, Yoshiki, A, Berberovic, Z, Bubshait, M, Cabezas, J, Carroll, T, Clark, G, Clarke, S, Creighton, A, Danisment, O, Eskandarian, M, Feugas, P, Gertsenstein, M, Guo, R, Hunter, J, Jacob, E, Lan, Q, Laurin, V, Law, N, MacMaster, S, Miller, D, Morikawa, L, Newbigging, S, Owen, C, Penton, P, Pereira, M, Qu, D, Shang, X, Sleep, G, Sohel, K, Tondat, S, Wang, Y, Vukobradovic, I, Zhu, Y, Chiani, F, Di Pietro, C, Di Segni, G, Ermakova, O, Ferrara, F, Fruscoloni, P, Gambadoro, A, Gastaldi, S, Golini, E, Sala, G L, Mandillo, S, Marazziti, D, Massimi, M, Matteoni, R, Orsini, T, Pasquini, M, Raspa, M, Rauch, A, Rossi, G, Rossi, N, Putti, S, Scavizzi, F, Tocchini-Valentini, G D, Beig, J, Bürger, A, Giesert, F, Graw, J, Kühn, R, Oritz, O, Schick, J, Seisenberger, C, Amarie, O, Garrett, L, Hölter, S M, Zimprich, A, Aguilar-Pimentel, A, Beckers, J, Brommage, R, Calzada-Wack, J, Fuchs, H, Gailus-Durner, V, Lengger, C, Leuchtenberger, S, Maier, H, Marschall, S, Moreth, K, Neff, F, Östereicher, M A, Rozman, J, Steinkamp, R, Stoeger, C, Treise, I, Stoeger, T, Yildrim, A Ö, Eickelberg, O, Becker, L, Klopstock, T, Ollert, M, Busch, D H, Schmidt-Weber, C, Bekeredjian, R, Zimmer, A, Rathkolb, B, Wolf, E, Klingenspor, M, Tocchini-Valentini, G P, Gao, X, Bradley, A, Skarnes, W C, Moore, M, Beaudet, A L, Justice, M J, Seavitt, J, Dickinson, M E, Wurst, W, De Angelis, M H, Herault, Y, Wakana, S, Nutter, L M J, Flenniken, A M, McKerlie, C, Murray, S A, Svenson, K L, Braun, R E, West, D B, Lloyd, K C K, Adams, D J, White, J, Karp, N, Flicek, P, Smedley, D, Meehan, T F, Parkinson, H E, Teboul, L M, Wells, S, Steel, K P, Mallon, A M & Brown, S D M 2017, ' A large scale hearing loss screen reveals an extensive unexplored genetic landscape for auditory dysfunction ', Nature Communications, vol. 8, 886 . https://doi.org/10.1038/s41467-017-00595-4, Nature communications, vol 8, iss 1
Publication Year :
2017
Publisher :
Nature Publishing Group, 2017.

Abstract

The developmental and physiological complexity of the auditory system is likely reflected in the underlying set of genes involved in auditory function. In humans, over 150 non-syndromic loci have been identified, and there are more than 400 human genetic syndromes with a hearing loss component. Over 100 non-syndromic hearing loss genes have been identified in mouse and human, but we remain ignorant of the full extent of the genetic landscape involved in auditory dysfunction. As part of the International Mouse Phenotyping Consortium, we undertook a hearing loss screen in a cohort of 3006 mouse knockout strains. In total, we identify 67 candidate hearing loss genes. We detect known hearing loss genes, but the vast majority, 52, of the candidate genes were novel. Our analysis reveals a large and unexplored genetic landscape involved with auditory function.<br />The full extent of the genetic basis for hearing impairment is unknown. Here, as part of the International Mouse Phenotyping Consortium, the authors perform a hearing loss screen in 3006 mouse knockout strains and identify 52 new candidate genes for genetic hearing loss.

Details

Language :
English
Database :
OpenAIRE
Journal :
Nat. Commun. 8:886 (2017), Nature Communications, Vol 8, Iss 1, Pp 1-11 (2017), Nature Communications, Bowl, M R, Simon, M M, Ingham, N J, Greenaway, S, Santos, L, Cater, H, Taylor, S, Mason, J, Kurbatova, N, Pearson, S, Bower, L R, Clary, D A, Meziane, H, Reilly, P, Minowa, O, Kelsey, L, Allen, S, Clementson-Mobbs, S, Codner, G, Fray, M, Gardiner, W, Joynson, R, Kenyon, J, Loeffler, J, Nell, B, Parker, A, Quwailid, D, Stewart, M, Walling, A, Zaman, R, Chen, C K, Conte, N, Matthews, P, Relac, M, Tudose, I, Warren, J, Le Marchand, E, El Amri, A, El Fertak, L, Ennah, H, Ali-Hadji, D, Ayadi, A, Wattenhofer-Donze, M, Moulaert, D, Jacquot, S, André, P, Birling, M C, Pavlovic, G, Lalanne, V, Lux, A, Riet, F, Mittelhaeuser, C, Bour, R, Guimond, A, Bam'Hamed, C, Leblanc, S, Vasseur, L, Selloum, M, Sorg, T, Ayabe, S, Furuse, T, Kaneda, H, Kobayashi, K, Masuya, H, Miura, I, Obata, Y, Suzuki, T, Tamura, M, Tanaka, N, Yamada, I, Yoshiki, A, Berberovic, Z, Bubshait, M, Cabezas, J, Carroll, T, Clark, G, Clarke, S, Creighton, A, Danisment, O, Eskandarian, M, Feugas, P, Gertsenstein, M, Guo, R, Hunter, J, Jacob, E, Lan, Q, Laurin, V, Law, N, MacMaster, S, Miller, D, Morikawa, L, Newbigging, S, Owen, C, Penton, P, Pereira, M, Qu, D, Shang, X, Sleep, G, Sohel, K, Tondat, S, Wang, Y, Vukobradovic, I, Zhu, Y, Chiani, F, Di Pietro, C, Di Segni, G, Ermakova, O, Ferrara, F, Fruscoloni, P, Gambadoro, A, Gastaldi, S, Golini, E, Sala, G L, Mandillo, S, Marazziti, D, Massimi, M, Matteoni, R, Orsini, T, Pasquini, M, Raspa, M, Rauch, A, Rossi, G, Rossi, N, Putti, S, Scavizzi, F, Tocchini-Valentini, G D, Beig, J, Bürger, A, Giesert, F, Graw, J, Kühn, R, Oritz, O, Schick, J, Seisenberger, C, Amarie, O, Garrett, L, Hölter, S M, Zimprich, A, Aguilar-Pimentel, A, Beckers, J, Brommage, R, Calzada-Wack, J, Fuchs, H, Gailus-Durner, V, Lengger, C, Leuchtenberger, S, Maier, H, Marschall, S, Moreth, K, Neff, F, Östereicher, M A, Rozman, J, Steinkamp, R, Stoeger, C, Treise, I, Stoeger, T, Yildrim, A Ö, Eickelberg, O, Becker, L, Klopstock, T, Ollert, M, Busch, D H, Schmidt-Weber, C, Bekeredjian, R, Zimmer, A, Rathkolb, B, Wolf, E, Klingenspor, M, Tocchini-Valentini, G P, Gao, X, Bradley, A, Skarnes, W C, Moore, M, Beaudet, A L, Justice, M J, Seavitt, J, Dickinson, M E, Wurst, W, De Angelis, M H, Herault, Y, Wakana, S, Nutter, L M J, Flenniken, A M, McKerlie, C, Murray, S A, Svenson, K L, Braun, R E, West, D B, Lloyd, K C K, Adams, D J, White, J, Karp, N, Flicek, P, Smedley, D, Meehan, T F, Parkinson, H E, Teboul, L M, Wells, S, Steel, K P, Mallon, A M & Brown, S D M 2017, ' A large scale hearing loss screen reveals an extensive unexplored genetic landscape for auditory dysfunction ', Nature Communications, vol. 8, 886 . https://doi.org/10.1038/s41467-017-00595-4, Nature communications, vol 8, iss 1
Accession number :
edsair.doi.dedup.....7f77ae2af84f093286e7804c4a997406
Full Text :
https://doi.org/10.1038/s41467-017-00595-4