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Prognostic predictive value of gene mutations in Japanese patients with hypertrophic cardiomyopathy

Authors :
Masaya Sugimoto
Hiroki Sato
Tsutomu Nishizawa
Shigeaki Nonoyama
Yoichi Kawamura
Shigeru Tateno
Yoshiyuki Furutani
Ayako Chida
Shinya Fuji
Masatoshi Kawana
Fukiko Ichida
Toshio Nakanishi
Mitsuyo Shimada
Mamoru Ayusawa
Takashi Soga
Hirokuni Yamazawa
Kenji Kuraishi
Masako Fujiwara
Rumiko Matsuoka
Mitsuhiro Nishimura
Kei Inai
Eriko Shimada
Michiko Furutani
Shigetoyo Kogaki
Jun Ishihara
Source :
Heart and Vessels. 32:700-707
Publication Year :
2016
Publisher :
Springer Science and Business Media LLC, 2016.

Abstract

Although some studies have attempted to find useful prognostic factors in hypertrophic cardiomyopathy (HCM), those results are not fully helpful for use in actual clinical practice. Furthermore, several genetic abnormalities associated with HCM have been identified. However, the genotype-phenotype correlation in HCM remains to be elucidated. Here, we attempted to assess patients with different types of gene mutations causing HCM and investigate the prognosis. A total of 140 patients with HCM underwent a screening test for myofilament gene mutations by direct sequencing of eight sarcomeric genes. Patients with a single mutation in cardiac troponin T, cardiac troponin I, α-tropomyosin, and regulatory and essential light chains were excluded from the study because the number of cases was too small. The clinical presentations and outcomes of the remaining 127 patients with HCM, 31 β-myosin heavy chain (MYH7) mutation carriers, 19 cardiac myosin-binding protein C (MYBPC3) mutation carriers, and 77 mutation non-carriers were analyzed retrospectively. MYBPC3 mutation carriers had a high frequency of ventricular arrhythmia and syncope. Kaplan-Meier curves revealed no significant difference in prognosis among the three groups, but a lack of family history of sudden death (SD) and a past history of syncope were significantly related to poor prognosis. An absence of family history of SD and past history of syncope are useful prognostic factors in patients with HCM. MYH7 and MYBPC3 mutations did not significantly influence prognosis compared to non-carriers. However, patients with the MYBPC3 mutation should be closely followed for the possibility of SD.

Details

ISSN :
16152573 and 09108327
Volume :
32
Database :
OpenAIRE
Journal :
Heart and Vessels
Accession number :
edsair.doi.dedup.....897eaf3f57af35067fc8138c6a7a0b30