Dural Arteriovenous Fistula Presenting with Purely Contralateral Ophthalmic Manifestations

Purpose: To report a case of dural arteriovenous fistula presenting with purely contralateral ophthalmic manifestations. Design: Interventional case report. Results: A 70-year-old male presenting with right-sided proptosis, injection, and choroidal effusions with a completely quiet fellow eye was found to have a left-sided dural arteriovenous fistula. After recognition on cerebral angiography, successful endovascular embolization was achieved, along with complete resolution of the contralateral ocular signs. Conclusions: Entirely unilateral ocular signs suggestive of an intracranial arteriovenous fistula may herald the presence of a contralateral vascular lesion.