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Obsessive Compulsive Symptoms and Psychopathological Profile in Children and Adolescents with KBG syndrome

Authors :
Paolo Alfieri
Francesco Demaria
Serena Licchelli
Ornella Santonastaso
Cristina Caciolo
Maria Cristina Digilio
Lorenzo Sinibaldi
Chiara Leoni
Maria Gnazzo
Marco Tartaglia
Patrizio Pasqualetti
Stefano Vicari
Source :
Brain Sciences, Vol 9, Iss 11, p 313 (2019)
Publication Year :
2019
Publisher :
MDPI AG, 2019.

Abstract

KBG syndrome is a rare multisystem developmental disorder caused by ankyrin repeat domain-containing protein 11 (ANKRD11) gene haploinsufficiency, resulting from either intragenic loss-of-function mutations or microdeletions encompassing the gene. Concerning the behavioral phenotype, a limited amount of research has been focused on attention deficit and hyperactivity disorder, autistic-like features, anxiety and impairments in emotion regulation, and no study has provided a systematic assessment. The aim of the present work is to investigate the psychopathological profile in children, adolescents, and young adults with KBG syndrome. Seventeen subjects with molecularly confirmed diagnoses were evaluated to investigate cognitive abilities and psychopathological features. Parametric and nonparametric indexes were used to describe the patient cohort according to type and distribution of specific measures. The KBG subjects were characterized by a low mean IQ score, with a distribution characterized by a variability similar to that occurring in the general population. Prevalence of neuropsychiatric disorders were computed as well as the corresponding confidence intervals to compare their prevalence to that reported for the general population. The KBG subjects were characterized by higher prevalence of obsessive-compulsive, tic, depressive and attention deficit and hyperactivity disorders. Obsessive-compulsive disorder is a peculiar aspect characterizing the psychopathological profile of KBG patients, which does not seem to be related to the cognitive level. The present study provides new relevant information towards the definition of a psychopathological phenotype of KBG syndromes useful to plan a better treatment for patients.

Details

Language :
English
ISSN :
20763425
Volume :
9
Issue :
11
Database :
Directory of Open Access Journals
Journal :
Brain Sciences
Publication Type :
Academic Journal
Accession number :
edsdoj.1dc163907e4037a56395c03d5b9d6a
Document Type :
article
Full Text :
https://doi.org/10.3390/brainsci9110313