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PCM1 is necessary for focal ciliary integrity and is a candidate for severe schizophrenia

Authors :
Tanner O. Monroe
Melanie E. Garrett
Maria Kousi
Ramona M. Rodriguiz
Sungjin Moon
Yushi Bai
Steven C. Brodar
Karen L. Soldano
Jeremiah Savage
Thomas F. Hansen
Donna M. Muzny
Richard A. Gibbs
Lawrence Barak
Patrick F. Sullivan
Allison E. Ashley-Koch
Akira Sawa
William C. Wetsel
Thomas Werge
Nicholas Katsanis
Source :
Nature Communications, Vol 11, Iss 1, Pp 1-14 (2020)
Publication Year :
2020
Publisher :
Nature Portfolio, 2020.

Abstract

The role of ciliary/centriolar components in the postnatal brain is unclear. Here, the authors show via ablation of Pcm1 in mice that degenerative ciliary/centriolar phenotypes induce neuroanatomical and behavioral changes. Sequencing of PCM1 in human cohorts and zebrafish in vivo complementation suggests PCM1 mutations can contribute to schizophrenia.

Subjects

Subjects :
Science

Details

Language :
English
ISSN :
20411723
Volume :
11
Issue :
1
Database :
Directory of Open Access Journals
Journal :
Nature Communications
Publication Type :
Academic Journal
Accession number :
edsdoj.5f60ef175b64f618a0d4c6e80cba746
Document Type :
article
Full Text :
https://doi.org/10.1038/s41467-020-19637-5