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Rare variants with large effects provide functional insights into the pathology of migraine subtypes, with and without aura

Authors :
Bjornsdottir, Gyda
Chalmer, Mona A.
Stefansdottir, Lilja
Skuladottir, Astros Th
Einarsson, Gudmundur
Andresdottir, Margret
Beyter, Doruk
Ferkingstad, Egil
Gretarsdottir, Solveig
Halldorsson, Bjarni V.
Halldorsson, Gisli H.
Helgadottir, Anna
Helgason, Hannes
Hjorleifsson Eldjarn, Grimur
Jonasdottir, Adalbjorg
Jonasdottir, Aslaug
Jonsdottir, Ingileif
Knowlton, Kirk U.
Nadauld, Lincoln D.
Lund, Sigrun H.
Magnusson, Olafur Th
Melsted, Pall
Moore, Kristjan H.S.
Oddsson, Asmundur
Olason, Pall I.
Sigurdsson, Asgeir
Banasik, Karina
Brunak, Søren
Didriksen, Maria
Kogelman, Lisette J.A.
Nielsen, Kaspar R.
Sørensen, Erik
Pedersen, Ole B.
Ullum, Henrik
Bay, Jakob
Burgdorf, Kristoffer
Dowsett, Joseph
Hjalgrim, Henrik
Jacobsen, Rikke L.
Louloudis, Ioannis
Lundgaard, Agnete
Mikkelsen, Christina
Nyegaard, Mette
Henriksen, Alexander P.
Werge, Thomas
Westergaard, David
Olesen, Jes
Ostrowski, Sisse R.
Hansen, Thomas F.
Bjornsdottir, Gyda
Chalmer, Mona A.
Stefansdottir, Lilja
Skuladottir, Astros Th
Einarsson, Gudmundur
Andresdottir, Margret
Beyter, Doruk
Ferkingstad, Egil
Gretarsdottir, Solveig
Halldorsson, Bjarni V.
Halldorsson, Gisli H.
Helgadottir, Anna
Helgason, Hannes
Hjorleifsson Eldjarn, Grimur
Jonasdottir, Adalbjorg
Jonasdottir, Aslaug
Jonsdottir, Ingileif
Knowlton, Kirk U.
Nadauld, Lincoln D.
Lund, Sigrun H.
Magnusson, Olafur Th
Melsted, Pall
Moore, Kristjan H.S.
Oddsson, Asmundur
Olason, Pall I.
Sigurdsson, Asgeir
Banasik, Karina
Brunak, Søren
Didriksen, Maria
Kogelman, Lisette J.A.
Nielsen, Kaspar R.
Sørensen, Erik
Pedersen, Ole B.
Ullum, Henrik
Bay, Jakob
Burgdorf, Kristoffer
Dowsett, Joseph
Hjalgrim, Henrik
Jacobsen, Rikke L.
Louloudis, Ioannis
Lundgaard, Agnete
Mikkelsen, Christina
Nyegaard, Mette
Henriksen, Alexander P.
Werge, Thomas
Westergaard, David
Olesen, Jes
Ostrowski, Sisse R.
Hansen, Thomas F.
Source :
Bjornsdottir , G , Chalmer , M A , Stefansdottir , L , Skuladottir , A T , Einarsson , G , Andresdottir , M , Beyter , D , Ferkingstad , E , Gretarsdottir , S , Halldorsson , B V , Halldorsson , G H , Helgadottir , A , Helgason , H , Hjorleifsson Eldjarn , G , Jonasdottir , A , Jonasdottir , A , Jonsdottir , I , Knowlton , K U , Nadauld , L D , Lund , S H , Magnusson , O T , Melsted , P , Moore , K H S , Oddsson , A , Olason , P I , Sigurdsson , A , Banasik , K , Brunak , S , Didriksen , M , Kogelman , L J A , Nielsen , K R , Sørensen , E , Pedersen , O B , Ullum , H , Bay , J , Burgdorf , K , Dowsett , J , Hjalgrim , H , Jacobsen , R L , Louloudis , I , Lundgaard , A , Mikkelsen , C , Nyegaard , M , Henriksen , A P , Werge , T , Westergaard , D , Olesen , J , Ostrowski , S R , Hansen , T F & DBDS Genetic Consortium 2023 , ' Rare variants with large effects provide functional insights into the pathology of migraine subtypes, with and without aura ' , Nature Genetics , vol. 55 , no. 11 , pp. 1843-1853 .
Publication Year :
2023

Abstract

Migraine is a complex neurovascular disease with a range of severity and symptoms, yet mostly studied as one phenotype in genome-wide association studies (GWAS). Here we combine large GWAS datasets from six European populations to study the main migraine subtypes, migraine with aura (MA) and migraine without aura (MO). We identified four new MA-associated variants (in PRRT2, PALMD, ABO and LRRK2) and classified 13 MO-associated variants. Rare variants with large effects highlight three genes. A rare frameshift variant in brain-expressed PRRT2 confers large risk of MA and epilepsy, but not MO. A burden test of rare loss-of-function variants in SCN11A, encoding a neuron-expressed sodium channel with a key role in pain sensation, shows strong protection against migraine. Finally, a rare variant with cis-regulatory effects on KCNK5 confers large protection against migraine and brain aneurysms. Our findings offer new insights with therapeutic potential into the complex biology of migraine and its subtypes.

Details

Database :
OAIster
Journal :
Bjornsdottir , G , Chalmer , M A , Stefansdottir , L , Skuladottir , A T , Einarsson , G , Andresdottir , M , Beyter , D , Ferkingstad , E , Gretarsdottir , S , Halldorsson , B V , Halldorsson , G H , Helgadottir , A , Helgason , H , Hjorleifsson Eldjarn , G , Jonasdottir , A , Jonasdottir , A , Jonsdottir , I , Knowlton , K U , Nadauld , L D , Lund , S H , Magnusson , O T , Melsted , P , Moore , K H S , Oddsson , A , Olason , P I , Sigurdsson , A , Banasik , K , Brunak , S , Didriksen , M , Kogelman , L J A , Nielsen , K R , Sørensen , E , Pedersen , O B , Ullum , H , Bay , J , Burgdorf , K , Dowsett , J , Hjalgrim , H , Jacobsen , R L , Louloudis , I , Lundgaard , A , Mikkelsen , C , Nyegaard , M , Henriksen , A P , Werge , T , Westergaard , D , Olesen , J , Ostrowski , S R , Hansen , T F & DBDS Genetic Consortium 2023 , ' Rare variants with large effects provide functional insights into the pathology of migraine subtypes, with and without aura ' , Nature Genetics , vol. 55 , no. 11 , pp. 1843-1853 .
Notes :
application/pdf, English
Publication Type :
Electronic Resource
Accession number :
edsoai.on1414369240
Document Type :
Electronic Resource